Owshalimpur D, Arbogast CB, Olson SW.
Chronological Serum Anti-Neutrophil Cytoplasmic Autoantibodies Prior
to the Clinical Presentation of Wegener's Granulomatosis.
ASN Annual Meeting -- San Diego
J Am Soc Nephrol
(Nov) 20:408A 2009

Background: The pathophysiology of Wegener's Granulomatosis (WG) has
yet to be completely elucidated. Although in vitro, animal, and case
report literature suggests a causal role for antinuclear cytoplasmic antibody
(ANCA), clinical studies have confirmed only an association. Seronegative WG
and a varied clinical spectrum of WG support a more complex disease
mechanism.
Methods: We compared chronologic ANCA titers in 52
patients with known WG prior to disease presentation to those in 52
healthy age, sex, race, and age of serum sample matched controls using the
Department of Defense Serum Repository (DoD SR). DoD SR comprises biannual
serum samples dating back to 1990 from all active duty military personnel
beginning on entrance to the military after a complete physical and
laboratory evaluation.
Results: Forty-two percent of diseased
subjects (DS) had a PR3 >6 U/mL prior to diagnosis vs 0% of healthy
controls (HC) (p= 0.0001). There is a larger percent of DS than HC with an
elevated PR3 >6 in the first quartile 1-239 days (64% vs. 0%; p=0.0001)
and the second quartile 239-569 days prior to diagnosis (36.4% vs. 0%;
p=0.0046). Fifty-four percent of DS had a PR3 >1 prior to diagnosis vs 2%
in HC (p <0.0001). The sensitivity and specificity of an index serum
sample PR3 >0 for future WG diagnosis were 71% and 54% respectively
(PPV/NPV of 61%/65%). The sensitivity and specificity of index serum sample
PR3 >2 were 15% and 100% respectively (PPV/NPV of
15%/100%).
Conclusion: PR3 is significantly elevated up to 1.5
years prior to WG diagnosis. A stable detectable PR3 level of >1 is
associated with a significant increased future incidence of WG. Data suggests
a 'two hit' theory with a baseline antibody production capability exacerbated
by a secondary stimulus triggering pathologic antibody levels and clinical
disease.

© Copyright 2009-2010 American Society of
Nephrology.Reproduced with permission.
Until September of 2010 all ASN
abstracts from the 2009 Annual Meeting are available at this link.
Disclaimer: Abstracts often have errors, both
typographical and otherwise. This posting is an electronic translation of
submitted abstracts which has not been verified against the original
submitted abstract nor with the authors for accuracy. As a result, there
may be errors, especially with regard to drug doses, but not limited to
these. Abstracts undergo only limited review, and data often are changed
as a result of the peer review process, so their reliability is less than
manuscripts published in peer-reviewed journals. In using these
summaries, you are agreeing that you are aware of these limitations.
The materials are provided on an as-is basis without any warranty of
any kind, either express or implied. In addition to errors, the
information presented may be incomplete or outdated.
The information contained is not intended nor recommended as a substitute
for professional medical advice. You are advised to check the appropriate
medical literature and the product information currently provided by the
manufacturer of each device to be used or drug to be administered to
verify the dosage, the method and duration of administration, or
contraindications. It is the responsibility of the treating physician or
other health care professional, relying on independent experience and
knowledge of the patient, to determine drug, disease, and the best
treatment for the patient.
To the fullest extent permitted by law, HDCN, ASN and their affiliates and
suppliers disclaim all
warranties, express or implied, including, but not limited to, any
warranty of merchantability, non- infringement or fitness for a
particular purpose.
In no event shall HDCN, ASN, or their affiliates or suppliers be
liable for any damages whatsoever (including, but not limited to,
direct, indirect, incidental, consequential, punitive or exemplary
damages, or any damages for loss of profits, use, data, goodwill or
other intangibles) arising from or in any way relating to these terms,
the materials, or any information, goods or services obtained from or
referred to in the materials, whether based on warranty, contract, tort
(including, but not limited to, negligence), or any other legal theory,
and whether or not any or all of the limited entities is advised of the
possibility of such damages.
|