Mehrotra R, Nolph KD, Kathuria P, Dotson L
Hypokalemic metabolic alkalosis with hypomagnesuric
hypermagnesemia and severe hypocalciuria: a new syndrome?
Am J Kidney Dis
(Jan) 29:106-114 1997

The authors report a 44-year-old man with hypokalemia who they
believe may have a new tubular disease distinct from Bartter's and
Gitelman's syndromes. This patient had hypokalemia (K 2.8-3.0
meq/L), metabolic alkalosis, mild azotemia (creat clearance 59
ml/min), hypocalciuria (FE Ca 0.08%) with normocalcemia,
hypomagnesuria (FE Mg 3.2-5.2%) with hypermagnesemia (Mg 2.1-2.8
meq/L), normal PTH levels, and glucosuria. Secondary aldosteronism
was also present. Clearance studies done during oral water loading
revealed normal sodium and water handling in both the thick
ascending limb of Henle (TALH) and distal tubule, but evidence for
a defect in proximal tubule reabsorption (glucosuria, supranormal
water clearance, and high distal delivery). After administration
of furosemide, calcium and magnesium excretions increased 30- and
5-fold, respectively. The authors postulate a proximal tubular
defect in NaCl reabsorption leading to hypocalciuria,
hypomagnesuria, and potassium wasting. Increased calcium and
magnesium reabsorption in the TALH (which are reversed by
furosemide) may be passive processes secondary to chronic volume
contraction.
Comment: This is an interesting study, and the details of the
clearance studies will be of interest to those who enjoy classical
clinical tubular physiology. It is clear that this patient does
not have either Gitelman's or Bartter's syndromes becuase of the
hypermagnesemia. Indeed, as the authors point out, hypermagnesemia
is very unusual in the absence of severe renal failure (or
exogenous magnesium administration). Serum magnesium levels were
2.1-2.8 mEq/L, and fractional excretion was 3.2-5.2%, which is
remarkably low in the face of hypermagnesemia. In CRF, FE Mg
should exceed 50% before hypermagnesemia occurs. Thus, these
findings cannot be explained by the mild CRF seen in this patient.
(David J. Leehey, M.D., Loyola University at Chicago)
The abstract to this paper is available from the NKF at
this site.